Affiliations 

  • 1 Laboratorio Genetica Umana, IRCCS Istituto Giannina Gaslini, 16147 Genova, Italy
  • 2 Centro Microcitemia e Anemie Congenite, Ospedali Galliera, 16128 Genova, Italy
  • 3 Medicina di Laboratorio, Azienda ULSS 2 Marca Trevigiana, 31100 Treviso, Italy
  • 4 Genetica e Biologia Molecolare ASO S. Croce e Carle, 12100 Cuneo, Italy
  • 5 Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, 20122 Milano, Italy
  • 6 Formerly, Servizio di Immunoematologia e Medicina Trasfusionale, A.O. Santa Maria degli Angeli, 33170 Pordenone, Italy
  • 7 Formerly Laboratorio Analisi, ASL AT, 14100 Asti, Italy
  • 8 Medicina di Laboratorio, Ospedale S. Bortolo, AULSS 8 Berica, 36100 Vicenza, Italy
  • 9 U.O. Diagnostica Ematochimica, Azienda Ospedaliero-Universitaria, 43126 Parma, Italy
  • 10 Sebia-Italia S.r.l., 50012 Bagno a Ripoli, Italy
  • 11 Formerly, Laboratorio Genetica Umana, Galliera Hospital, 16128 Genova, Italy
Genes (Basel), 2021 11 19;12(11).
PMID: 34828427 DOI: 10.3390/genes12111821

Abstract

BACKGROUND: Hemoglobin A (Hb A) (α2β2) in the normal adult subject constitutes 96-98% of hemoglobin, and Hb F is normally less than 1%, while for hemoglobin A2 (Hb A2) (α2δ2), the normal reference values are between 2.0 and 3.3%. It is important to evaluate the presence of possible delta gene mutations in a population at high risk for globin gene defects in order to correctly diagnose the β-thalassemia carrier.

METHODS: The most used methods for the quantification of Hb A2 are based on automated high performance liquid chromatography (HPLC) or capillary electrophoresis (CE). In particular Hb analyses were performed by HPLC on three dedicated devices. DNA analyses were performed according to local standard protocols.

RESULTS: Here, we described eight new δ-globin gene variants discovered and characterized in some laboratories in Northern Italy in recent years. These new variants were added to the many already known Hb A2 variants that were found with an estimated frequency of about 1-2% during the screening tests in our laboratories.

CONCLUSIONS: The knowledge recognition of the delta variant on Hb analysis and accurate molecular characterization is crucial to provide an accurate definitive thalassemia diagnosis, particularly in young subjects who would like to ask for a prenatal diagnosis or preimplantation genetic diagnosis.

* Title and MeSH Headings from MEDLINE®/PubMed®, a database of the U.S. National Library of Medicine.